Cutaneous leishmaniasis (CL) is one of the mostcommon endemic diseases in Iran. It has a diversespectrum of clinical manifestations. Herein we presenta woman with leishmanial dactylitis, which is a veryrare clinical form of CL. Successful treatment consistedof parenteral pentavalent antimonials for two months.Leishmanial dactylitis can be easily misdiagnosedas bacterial or fungal infections, psoriasis, or evenmalignancies. Accordingly, it should be consideredin the differential diagnosis of dactylitis in endemicareas and in travelers from endemic countries.